18 years old patient with Bland White Garland syndrome after non‑ST segment elevation myocardial infarction (RCD code: I-1C.3)

Natalia Dłużniewska, Jakub Podolec, Magdalena Kostkiewicz, Lidia Tomkiewicz‑Pająk, Maria Olszowska, Piotr Podolec

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Abstract


Bland – White – Garland syndrome (or ALCAPA) is a rare coronary anomaly including anomalous origin of the left coronary artery from the pulmonary artery (ALCAPA). It occurs in 0,2-0,5% of all congenital cardiac malformations. Although it has high mortality rate of 90% within the newborn children. Ca. 10–15% of patients reach adulthood. In most cases the existence of extensive coronary collaterals is increasing  their chances to survive [5,6,7]. Usually adult patients with ALCAPA are asymptomatic. We present a case of an 18 years-old patient with Bland-White-Syndrome, who suffered an episode of non - ST segement elevation myocardial infarction and successfully treated with cardiac surgery. JRCD 2015; 2 (2): 26–29


Keywords


amyloidosis; heart failure; myeloma multiplex

References


Angelini P, Velasco JA, Flamm S. Coronary Anomalies Incidence, Pathophysiology, and Clinical Relevance. Circulation 2002; 105: 2449–2454.

Zemanek D, Veselka J, Kautznerova D, Tesar D. The anomalous origin of the left coronary artery from the right aortic sinus: is the coronary angiography still a ‘gold standard’?. The International Journal of Cardiovascular Imaging 2006; 22:1 27–133.

Yamanaka O, Hobbs RE. Coronary artery anomalies in 126,595 patients undergoing coronary arteriography. Cathet Cardiovasc Diagn. 1990; 21: 28–40.

Angelini P. Coronary Artery Anomalies An Entity in Search of an Identity. Circulation 2007; 115: 1296–1305.

Kim B, Park Y, Hong S et al. Anomalous origin of the left coronary artery from the pulmonary artery initially visualized by echocardiography and multidetector computed tomography coronary angiography. J Cardiovasc Ultrasound 2012; 20: 197–200.

Kumar RV, Rama Krishna LS, Ramachandran G. Anomalous origin of the left coronary artery arising from the pulmonary artery: Reverse remodeling of coronary arterie following translocation operations. Indian J Thorac Cardiovasc Surg 2012; 28: 151–152. Neony P, Beaune J, Champsaur G et al. Anomalous Origin of Left Coronary Artery From the Evolution of Left Ventricular Function and Perfusion 44‑Year‑Old Man Pulmonary Artery: After Surgery in a 44‑Year‑Old Man. Clin. Cardiol. 1992; 15: 466–468.

Bland EF, White PD, Garland J. Congenital anomalies of the coronary arteries: report of unusual case associated with cardiac hypertrophy. Am Heart Journal 1933; 8: 787.

Acikel S, Dogan M, Turkvatan A et al. Single left coronary artery and coronary sinus opening anomaly in patient presenting with cardiac symptoms. Canadian Journal of Cardiology 2012; 28: 612.e1.–612.e3.

Blaghith M. Anomalous origin of the right coronary artery from the proximal left anterior descending artery and a single coronary artety anomaly: Three case reports. Journal Sauid Heart Assoc. 2013; 25: 43–46.

Korosoglou G, Ringwald G, Giannitsis E, Katus H. Anomalous origin of the left circumflex coronary artery from the pulmonary arterty. A very rare congenital anomaly in an adult patient diagnosed by cardiovascular magnetic resonance. Journal of Cardiovascular Magnetic Resonance 2008; 10: 4.

Haponiuk I, Rycaj J, Grzybowski A et al. Leczenie operacyjne zespołu Blanda – White’a – Garlanda u noworodka z rozległym pozawałowym uszkodzeniem lewej komory. Czy korekcja jest bardziej korzystna od transplantacji serca? Folia Cardiol. 2004; 11: 687–696.

Kuroczynski W, Kampmann C, Kayhan N et al. Anomalous origin of the left coronary artery from the pulmonary artery: mid‑term results after surgical correction. Clin Res Cardiol. 2008; 97: 266–271.

Amaral F, Carvalho JS, Granzotti JA, Shinebourne EA. Anomalous Origin of the Left Coronary Artery from the Pulmonary Trunk. Clinical Features and Midterm Results after Surgical Treatment. Arq Bras Cardiol. 1999; 72: 314–320.




DOI: http://dx.doi.org/10.20418%2Fjrcd.vol2no2.165

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